Rhabdomyomatous mesenchymal hamartoma of the face causing trigeminal neuralgia

Leon Ray White, Vaidehi Agrawal, Lisa Sutton, Aiysha C. Balbosa

Research output: Contribution to journalArticle

Abstract

Objective: Unusual clinical course Background: Rhabdomyomatous mesenchymal hamartoma (RMH) is a benign, potentially pigmented lesion that occurs in the head and neck region. It generally consists of haphazardly arranged skeletal muscle with adipose tissue, blood vessels, collagen and nerve fibers and is largely asymptomatic. Trigeminal neuralgia is pain due to compression of the trigeminal nerve. TN may be idiopathic or associated with lesion-mediated compression. Case Report: We describe the case of a 14-year-old female presenting with trigeminal neuralgia (TN) associated with RMH. On initial consultation, the patient presented with a history of right-sided lower facial swelling, numbness, and pain. Evaluation by various specialists confirmed TN. Surgical resection of the lesion resolved the condition and pathology confirmed RMH. Conclusions: This is the first case report demonstrating RMH-mediated TN. Surgical resection of the RMH is a safe management approach for this diagnosis.

Original languageEnglish (US)
Pages (from-to)338-340
Number of pages3
JournalAmerican Journal of Case Reports
Volume16
DOIs
StatePublished - Jun 3 2015
Externally publishedYes

Fingerprint

Trigeminal Neuralgia
Hamartoma
Pain
Trigeminal Nerve
Hypesthesia
Nerve Fibers
Blood Vessels
Adipose Tissue
Skeletal Muscle
Neck
Collagen
Referral and Consultation
Head
Pathology

Keywords

  • Acute pain
  • Craniofacial abnormalities
  • Pediatrics
  • Trigeminal nerve

ASJC Scopus subject areas

  • Medicine(all)

Cite this

Rhabdomyomatous mesenchymal hamartoma of the face causing trigeminal neuralgia. / White, Leon Ray; Agrawal, Vaidehi; Sutton, Lisa; Balbosa, Aiysha C.

In: American Journal of Case Reports, Vol. 16, 03.06.2015, p. 338-340.

Research output: Contribution to journalArticle

White, Leon Ray ; Agrawal, Vaidehi ; Sutton, Lisa ; Balbosa, Aiysha C. / Rhabdomyomatous mesenchymal hamartoma of the face causing trigeminal neuralgia. In: American Journal of Case Reports. 2015 ; Vol. 16. pp. 338-340.
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