Atypical idiopathic orbital inflammation in a young girl

Jordan Spindle, Sherry Kalla, Baljeet Purewal, Roman Shinder

Research output: Contribution to journalArticle

Abstract

A 7-year-old girl presented with chronic right periocular pain worst in abduction, edema, and proptosis with radiographic evidence of right medial rectus myositis. After a negative workup, she was diagnosed and treated for idiopathic orbital inflammation (IOI) with a brisk response to oral steroids. She returned 8 months later with left periocular pain worst in abduction, proptosis, and radiographic evidence of left lateral rectus myositis. She was treated for recurrent and alternating IOI with intravenous (IV) glucocorticoids with resolution. One year later, she recurred with similar left orbital signs and symptoms and was found to have a left inferior oblique myositis on MRI. She was treated with oral steroids and methotrexate with clinical resolution. Ten months later, she presented with left periocular pain worst on adduction and was found to have left medial rectus myositis on MRI. She was treated with IV steroids, IV immunoglobulin, and rituximab with resolution of all symptoms. She is currently maintained on methotrexate and oral glucocorticoids. The atypical pediatric case of IOI over a 4-year period is described in this study.

Original languageEnglish (US)
JournalOphthalmic Plastic and Reconstructive Surgery
Volume29
Issue number3
DOIs
StatePublished - May 2013
Externally publishedYes

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Myositis
Inflammation
Exophthalmos
Steroids
Methotrexate
Pain
Glucocorticoids
Intravenous Immunoglobulins
Signs and Symptoms
Edema
Pediatrics

ASJC Scopus subject areas

  • Ophthalmology
  • Surgery

Cite this

Atypical idiopathic orbital inflammation in a young girl. / Spindle, Jordan; Kalla, Sherry; Purewal, Baljeet; Shinder, Roman.

In: Ophthalmic Plastic and Reconstructive Surgery, Vol. 29, No. 3, 05.2013.

Research output: Contribution to journalArticle

Spindle, Jordan ; Kalla, Sherry ; Purewal, Baljeet ; Shinder, Roman. / Atypical idiopathic orbital inflammation in a young girl. In: Ophthalmic Plastic and Reconstructive Surgery. 2013 ; Vol. 29, No. 3.
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